Gene-centered representation of coding and regulatory variation enables outcome prediction
Sokolova, K.; Kristensen, V.; Park, C. Y.; Theesfeld, C.; Mariani, L.; Kretzler, M.; Troyanskaya, O. G.; Cure Glomerulonephropathy (CureGN) Study Consortium,
Show abstract
Integrating coding and regulatory variation into unified, interpretable representations remains a challenge in functional genomics. Current approaches either focus on common variants or analyze individual variants in isolation, missing the cumulative, cell-type-specific impact of both coding and noncoding variants on each gene. We present Volaria, a computational framework that integrates coding and regulatory genetic variation into unified, gene-centered representations for disease outcome prediction from whole-genome sequencing. Volaria leverages deep learning models to capture variant effects on cell-type-specific gene expression and integrates them with AI-predicted exonic variant pathogenicity to produce representations that capture the cumulative effect of genome-wide rare and common variation. Applied to whole genomes of individuals with rare glomerular diseases, Volaria predicts individual outcomes directly from germline sequence, demonstrating that structured, cell-type-aware representations capture predictive signals beyond population-based polygenic risk scores and unstructured representations. Importantly, the framework identifies context-specific biological mechanisms, providing interpretability that can be aligned with clinical measurements. By encoding genome-wide variation into compact and biologically grounded representations, Volaria provides a scalable foundation for genome interpretation and individualized outcome modeling from germline sequence, complementing phenotypic and clinical information in the future integrative frameworks.
Matching journals
The top 5 journals account for 50% of the predicted probability mass.
Similar papers in this journal
- Common genetic variation associated with Mendelian disease severity revealed through cryptic phenotype analysis 95%
- The chromatin landscape of healthy and injured cell types in the human kidney 94%
- Single cell transcriptional and chromatin accessibility profiling redefine cellular heterogeneity in the adult human kidney 94%
Similar papers in this journal
- Leveraging genomic diversity for discovery in an EHR-linked biobank: the UCLA ATLAS Community Health Initiative 93%
- Diagnostic Evidence GAuge of Single cells (DEGAS): A flexible deep-transfer learning framework for prioritizing cells in relation to disease 92%
- Genome-wide prediction of pathogenic gain- and loss-of-function variants from ensemble learning of diverse feature set 92%
Similar papers in this journal
- Reduced nephron endowment in the common Six2-TGCtg mouse line is due to Six3 misexpression by aberrant enhancer-promoter interactions in the transgene 93%
- Kidney single-cell atlas reveals myeloid heterogeneity in progression and regression of kidney disease. 93%
- Enriched Single-Nucleus RNA-Sequencing reveals unique attributes of distal convoluted tubule cells 92%
Similar papers in this journal
- The functional impact of rare variation across the regulatory cascade 93%
- Proteome-wide Mendelian randomization in global biobank meta-analysis reveals multi-ancestry drug targets for common diseases 93%
- The UCLA ATLAS Community Health Initiative: promoting precision health research in a diverse biobank 93%
"Similar papers" are the closest papers from that journal in the model's embedding space. They show what the match is built on, but the ranking comes mostly from a classifier over the whole training set, not from these examples alone.